Identification of the Precise Developmental Window and Tissue Bed for the Somatic Mutation Causing Sturge Weber Syndrome
Abstract
Sturge Weber syndrome (SWS) is a sporadic, congenital, neuro-cutaneous disorder characterized by a capillary vascular malformation. The vascular malformation affects the skin in the distribution of the ophthalmic branch of the trigeminal nerve, and abnormal capillary venous vessels in the leptomeninges of the brain and choroid, leading to glaucoma, seizures, stroke, and intellectual disability. In 2013, a somatic mutation (c.548GA, p.R183Q) in GNAQ (encoding Gq) was identified in affected tissue from Sturge Weber Syndrome. This Gq signaling pathway has been extensively studied in other biological and disease (cancer) contexts, and thus, potential drugs are already available. In addition, novel therapies that target this pathway are currently under development in biotech/pharma drug pipelines. The discovery of the cause of Sturge Weber Syndrome as this specific somatic activating mutation brought great hope of a scientifically-based treatment.
Document Details
- Document Type
- Technical Report
- Publication Date
- May 01, 2023
- Accession Number
- AD1209090
Entities
People
- Douglas A Marchuk
Organizations
- Duke University